A carregar...

The human sex-reversing ATRX gene has a homologue on the marsupial Y chromosome, ATRY: Implications for the evolution of mammalian sex determination

Mutations in the ATRX gene on the human X chromosome cause X-linked α-thalassemia and mental retardation. XY patients with deletions or mutations in this gene display varying degrees of sex reversal, implicating ATRX in the development of the human testis. To explore further the role of ATRX in mamm...

ver descrição completa

Na minha lista:
Detalhes bibliográficos
Main Authors: Pask, Andrew, Renfree, Marilyn B., Marshall Graves, Jennifer A.
Formato: Artigo
Idioma:en
Publicado em: The National Academy of Sciences 2000
Assuntos:
Acesso em linha:https://ncbi.nlm.nih.gov/pmc/articles/PMC27202/
https://ncbi.nlm.nih.gov/pubmed/11069290
Tags: Adicionar Tag
Sem tags, seja o primeiro a adicionar uma tag!
id pubmed-27202
record_format dspace
spelling pubmed-272022001-03-17 The human sex-reversing ATRX gene has a homologue on the marsupial Y chromosome, ATRY: Implications for the evolution of mammalian sex determination Pask, Andrew Renfree, Marilyn B. Marshall Graves, Jennifer A. Proc Natl Acad Sci U S A Biological Sciences Mutations in the ATRX gene on the human X chromosome cause X-linked α-thalassemia and mental retardation. XY patients with deletions or mutations in this gene display varying degrees of sex reversal, implicating ATRX in the development of the human testis. To explore further the role of ATRX in mammalian sex differentiation, the homologous gene was cloned and characterized in a marsupial. Surprisingly, active homologues of ATRX were detected on the marsupial Y as well as the X chromosome. The Y-borne copy (ATRY) displays testis-specific expression. This, as well as the sex reversal of ATRX patients, suggests that ATRY is involved in testis development in marsupials and may represent an ancestral testis-determining mechanism that predated the evolution of SRY as the primary mammalian male sex-determining gene. There is no evidence for a Y-borne ATRX homologue in mouse or human, implying that this gene has been lost in eutherians and its role supplanted by the evolution of SRY from SOX3 as the dominant determiner of male differentiation. The National Academy of Sciences 2000-11-21 2000-11-07 /pmc/articles/PMC27202/ /pubmed/11069290 Text en Copyright © 2000, The National Academy of Sciences
institution US National Library of Medicine
collection PubMed Central
language en
format Article
topic Biological Sciences
spellingShingle Biological Sciences
Pask, Andrew
Renfree, Marilyn B.
Marshall Graves, Jennifer A.
The human sex-reversing ATRX gene has a homologue on the marsupial Y chromosome, ATRY: Implications for the evolution of mammalian sex determination
description Mutations in the ATRX gene on the human X chromosome cause X-linked α-thalassemia and mental retardation. XY patients with deletions or mutations in this gene display varying degrees of sex reversal, implicating ATRX in the development of the human testis. To explore further the role of ATRX in mammalian sex differentiation, the homologous gene was cloned and characterized in a marsupial. Surprisingly, active homologues of ATRX were detected on the marsupial Y as well as the X chromosome. The Y-borne copy (ATRY) displays testis-specific expression. This, as well as the sex reversal of ATRX patients, suggests that ATRY is involved in testis development in marsupials and may represent an ancestral testis-determining mechanism that predated the evolution of SRY as the primary mammalian male sex-determining gene. There is no evidence for a Y-borne ATRX homologue in mouse or human, implying that this gene has been lost in eutherians and its role supplanted by the evolution of SRY from SOX3 as the dominant determiner of male differentiation.
author Pask, Andrew
Renfree, Marilyn B.
Marshall Graves, Jennifer A.
author_facet Pask, Andrew
Renfree, Marilyn B.
Marshall Graves, Jennifer A.
author_sort Pask, Andrew
title The human sex-reversing ATRX gene has a homologue on the marsupial Y chromosome, ATRY: Implications for the evolution of mammalian sex determination
title_short The human sex-reversing ATRX gene has a homologue on the marsupial Y chromosome, ATRY: Implications for the evolution of mammalian sex determination
title_full The human sex-reversing ATRX gene has a homologue on the marsupial Y chromosome, ATRY: Implications for the evolution of mammalian sex determination
title_fullStr The human sex-reversing ATRX gene has a homologue on the marsupial Y chromosome, ATRY: Implications for the evolution of mammalian sex determination
title_full_unstemmed The human sex-reversing ATRX gene has a homologue on the marsupial Y chromosome, ATRY: Implications for the evolution of mammalian sex determination
title_sort human sex-reversing atrx gene has a homologue on the marsupial y chromosome, atry: implications for the evolution of mammalian sex determination
publisher The National Academy of Sciences
publisher_facet The National Academy of Sciences
publishDate 2000
url https://ncbi.nlm.nih.gov/pmc/articles/PMC27202/
https://ncbi.nlm.nih.gov/pubmed/11069290
_version_ 1758993754602078208